Metallopeptidase activities in hereditary angioedema: effect of androgen prophylaxis on plasma aminopeptidase P - PubMed
. 2008 Feb;121(2):429-33.
doi: 10.1016/j.jaci.2007.10.048. Epub 2007 Dec 26.
Anik Désormeaux, Josée Robillard, Denise Ponard, Laurence Bouillet, Ludovic Martin, Gisèle Kanny, Denise-Anne Moneret-Vautrin, Jean-Luc Bosson, Jean-Louis Quesada, Margarita López-Trascasa, Albert Adam
Affiliations
- PMID: 18158172
- PMCID: PMC4126900
- DOI: 10.1016/j.jaci.2007.10.048
Metallopeptidase activities in hereditary angioedema: effect of androgen prophylaxis on plasma aminopeptidase P
Christian Drouet et al. J Allergy Clin Immunol. 2008 Feb.
Abstract
Background: Aminopeptidase P (APP) plays an important role in the catabolism of kinins in human plasma, mostly for des-Arg(9)-bradykinin. Impaired degradation of this active bradykinin metabolite was found to be associated with a decreased APP activity in hypertensive patients who experienced angioedema while being treated with angiotensin I-converting enzyme inhibitors. The pathophysiology of hereditary angioedema is presently attributed only to a quantitative/qualitative C1 inhibitor (CI-INH) defect with increased bradykinin release.
Objectives: In the context of androgen prophylaxis, increased CI-INH function cannot fully explain protection from angioedema attacks alone because of the limited reversion of the CI-INH defects. Therefore we hypothesized that androgen prophylaxis could enhance plasma APP activity.
Methods: Patients with hereditary angioedema were investigated for plasma metallopeptidase activities responsible for kinin catabolism (APP, angiotensin I-converting enzyme, and carboxypeptidase N) and for CI-INH function in treated and untreated patients.
Results: APP activity was asymmetrically distributed in untreated patients (n = 147): the mean value was significantly lower than the value in a reference healthy and unmedicated population (n = 116; P < or = .001). Prophylaxis with androgen induced a significant increase in APP activity (P < or = .001), whereas it did not affect the other metallopeptidase activities. In both patient groups, APP activity showed a significant inverse relationship to disease severity (P < or = .001).
Conclusion: In addition to the effect on circulating CI-INH levels, the increase in APP levels brought on by androgens could contribute to a more effective control of the kinin accumulation considered to be responsible for the symptoms of angioedema.
Conflict of interest statement
Disclosure of potential conflict of interest: The authors have declared that they have no conflict of interest.
Figures

Distribution of APP activity in patients with HAE with no prophylaxis (solid columns, n = 147) and in healthy individuals used as the reference group (open columns, n = 116).

Plasma APP activity (A) and CI-INH serpin function (B) in patients treated with long-term androgen prophylaxis (200 mg of danazol or 4 mg of stanozolol per 1–4 days; solid symbols) or not treated (open symbols). Data are presented in box whisker plots showing the median (horizontal bars within boxes), the inter-quartile range (boxes), and the 5th to 95th percentiles (vertical bars). Values greater than and less than these levels were dotted separately. Data comparisons between groups of patients taking androgen or not are presented according to the Mann-Whitney or Student nonparametric tests.

Plasma APP activity and CI-INH serpin function of patients 1 and 2 with HAE undergoing short-term prophylaxis with danazol (400 and 600 mg/d, respectively, for 10 days). Differences between values observed in the context of danazol treatment (solid columns) or no treatment (open columns) are indicated as increasing factors.

CI-INH function or APP activity versus disease severity. Box whisker plots of CI-INH function (A and B) or APP activity (C and D) represent the median (horizontal bars within boxes) and the interquartile range (boxes) with the 5th to 95th percentiles (vertical bars). Data were expressed for each disease severity class (1–2, severe disease; 3–5, mild to asymptomatic disease) in patients with no treatment (n = 157; Fig 4, A and C) and those with androgen prophylaxis (n = 59; Fig 4, B and D). Data comparisons for severity of disease between groups follow the equality of means with the Student t test (Fig 4, B) or the Mann-Whitney rank sum test (Fig 4, A, C, and D).

Risk estimate for the association of the biologic parameters with disease severity. Odds ratios were calculated from plasma CI-INH function and APP, CPN, and ACE activity. A, Untreated patients (n = 98). B, Treated patients (n = 36). Dashed lines represent the 95% Cis, and vertical bars represent the median values.
Similar articles
-
Guo Y, Zhang H, Lai H, Wang H, Chong-Neto HJ, Valle SOR, Zhu R. Guo Y, et al. Orphanet J Rare Dis. 2022 Nov 2;17(1):399. doi: 10.1186/s13023-022-02536-x. Orphanet J Rare Dis. 2022. PMID: 36324138 Free PMC article. Review.
-
Suffritti C, Zanichelli A, Maggioni L, Bonanni E, Cugno M, Cicardi M. Suffritti C, et al. Clin Exp Allergy. 2014 Dec;44(12):1503-14. doi: 10.1111/cea.12293. Clin Exp Allergy. 2014. PMID: 24552232
-
Metabolism of bradykinin agonists and antagonists by plasma aminopeptidase P.
Ward PE, Chow A, Drapeau G. Ward PE, et al. Biochem Pharmacol. 1991 Jul 25;42(4):721-7. doi: 10.1016/0006-2952(91)90028-4. Biochem Pharmacol. 1991. PMID: 1651078
-
Distinct conditions support a novel classification for bradykinin-mediated angio-oedema.
Dessart P, Defendi F, Humeau H, Nicolie B, Sarre ME, Charignon D, Ponard D, Cichon S, Drouet C, Martin L. Dessart P, et al. Dermatology. 2015;230(4):324-31. doi: 10.1159/000371814. Epub 2015 Feb 20. Dermatology. 2015. PMID: 25720836
-
A Decade of Change: Recent Developments in Pharmacotherapy of Hereditary Angioedema (HAE).
Bork K. Bork K. Clin Rev Allergy Immunol. 2016 Oct;51(2):183-92. doi: 10.1007/s12016-016-8544-9. Clin Rev Allergy Immunol. 2016. PMID: 27207174 Review.
Cited by
-
Guo Y, Zhang H, Lai H, Wang H, Chong-Neto HJ, Valle SOR, Zhu R. Guo Y, et al. Orphanet J Rare Dis. 2022 Nov 2;17(1):399. doi: 10.1186/s13023-022-02536-x. Orphanet J Rare Dis. 2022. PMID: 36324138 Free PMC article. Review.
-
Ballonová L, Souček P, Slanina P, Réblová K, Zapletal O, Vlková M, Hakl R, Bíly V, Grombiříková H, Svobodová E, Kulíšková P, Štíchová J, Sobotková M, Zachová R, Hanzlíková J, Vachová M, Králíčková P, Krčmová I, Jeseňák M, Freiberger T. Ballonová L, et al. Front Genet. 2023 Jul 4;14:1123914. doi: 10.3389/fgene.2023.1123914. eCollection 2023. Front Genet. 2023. PMID: 37470035 Free PMC article.
-
Attenuated androgen discontinuation in patients with hereditary angioedema: a commented case series.
Maurer M, Magerl M, Aygören-Pürsün E, Bork K, Farkas H, Longhurst H, Kiani-Alikhan S, Bouillet L, Boccon-Gibod I, Cancian M, Zanichelli A, Launay D. Maurer M, et al. Allergy Asthma Clin Immunol. 2022 Jan 13;18(1):4. doi: 10.1186/s13223-021-00644-0. Allergy Asthma Clin Immunol. 2022. PMID: 35027083 Free PMC article.
-
Birmingham JM, Wisnivesky J, Busse PJ. Birmingham JM, et al. J Allergy Clin Immunol Glob. 2024 Feb 12;3(2):100226. doi: 10.1016/j.jacig.2024.100226. eCollection 2024 May. J Allergy Clin Immunol Glob. 2024. PMID: 38495866 Free PMC article.
-
Kininogen Cleavage Assay: Diagnostic Assistance for Kinin-Mediated Angioedema Conditions.
Baroso R, Sellier P, Defendi F, Charignon D, Ghannam A, Habib M, Drouet C, Favier B. Baroso R, et al. PLoS One. 2016 Sep 29;11(9):e0163958. doi: 10.1371/journal.pone.0163958. eCollection 2016. PLoS One. 2016. PMID: 27685806 Free PMC article.
References
-
- Nussberger J, Cugno M, Amstutz C, Cicardi M, Pellacani A, Agostoni A. Plasma bradykinin in angio-oedema. Lancet. 1998;351:1693–7. - PubMed
-
- Cugno M, Nussberger J, Cicardi M, Agostoni A. Bradykinin and the pathophysiology of angioedema. Int Immunopharmacol. 2003;3:311–7. - PubMed
-
- Davis AE., III The pathophysiology of hereditary angioedema. Clin Immunol. 2005;114:3–9. - PubMed
-
- Matthews KW, Mueller-Ortiz SL, Wetsel RA. Carboxypeptidase N: a pleiotropic regulator of inflammation. Mol Immunol. 2004;40:785–93. - PubMed
-
- Cyr M, Lepage Y, Blais C, Jr, Gervais N, Cugno M, Rouleau JL, et al. Bradykinin and des-Arg(9)-bradykinin metabolic pathways and kinetics of activation of human plasma. Am J Physiol Heart Circ Physiol. 2001;281:H275–83. - PubMed
Publication types
MeSH terms
Substances
LinkOut - more resources
Full Text Sources