Fine mapping of type 1 diabetes susceptibility loci and evidence for colocalization of causal variants with lymphoid gene enhancers - PubMed
doi: 10.1038/ng.3245. Epub 2015 Mar 9.
Wei-Min Chen 2 , Oliver Burren 3 , Nick J Cooper 3 , Aaron R Quinlan 2 , Josyf C Mychaleckyj 2 , Emily Farber 4 , Jessica K Bonnie 4 , Michal Szpak 4 , Ellen Schofield 3 , Premanand Achuthan 3 , Hui Guo 3 , Mary D Fortune 3 , Helen Stevens 3 , Neil M Walker 3 , Lucas D Ward 5 , Anshul Kundaje 6 , Manolis Kellis 5 , Mark J Daly 7 , Jeffrey C Barrett 8 , Jason D Cooper 3 , Panos Deloukas 8 ; Type 1 Diabetes Genetics Consortium; John A Todd 3 , Chris Wallace 9 , Patrick Concannon 4 , Stephen S Rich 2
Collaborators, Affiliations
- PMID: 25751624
- PMCID: PMC4380767
- DOI: 10.1038/ng.3245
Fine mapping of type 1 diabetes susceptibility loci and evidence for colocalization of causal variants with lymphoid gene enhancers
Suna Onengut-Gumuscu et al. Nat Genet. 2015 Apr.
Abstract
Genetic studies of type 1 diabetes (T1D) have identified 50 susceptibility regions, finding major pathways contributing to risk, with some loci shared across immune disorders. To make genetic comparisons across autoimmune disorders as informative as possible, a dense genotyping array, the Immunochip, was developed, from which we identified four new T1D-associated regions (P < 5 × 10(-8)). A comparative analysis with 15 immune diseases showed that T1D is more similar genetically to other autoantibody-positive diseases, significantly most similar to juvenile idiopathic arthritis and significantly least similar to ulcerative colitis, and provided support for three additional new T1D risk loci. Using a Bayesian approach, we defined credible sets for the T1D-associated SNPs. The associated SNPs localized to enhancer sequences active in thymus, T and B cells, and CD34(+) stem cells. Enhancer-promoter interactions can now be analyzed in these cell types to identify which particular genes and regulatory sequences are causal.
Conflict of interest statement
COMPETING FINANCIAL INTERESTS
The authors declare no competing financial interests.
Figures

T1D ImmunoChip p-value enrichment analysis. Panel (a) shows Z scores for densely typed regions against diseases curated in ImmunoBase. Diseases with positive Z scores indicate evidence for overall genetic overlap with T1D, within densely typed regions accessible on ImmunoChip. Those with negative scores indicate evidence for negative association. Each bar is labelled with the Wilcoxon rank sum test p-value and coloured by disease autoantibody positive/negative status. The MHC region (chr6:25Mb..35Mb GRCh37) was excluded from analysis. AA- Alopecia Areata, AS - Ankylosing Spondylitis ATD - Autoimmune thyroid disease,, CEL- Celiac disease, CD - Crohn’s disease, JIA - Juvenile Idiopathic Arthritis, MS - Multiple Sclerosis, NAR – Narcolepsy, PBC - Primary Biliary Cirrhosis, PSC- Primary Sclerosing Cholangitis PSO - Psoriasis, RA - Rheumatoid Arthritis, SJO – Sjogren’s syndrome, SLE Systemic Lupus Erythematosus, UC - Ulcerative Colitis. Panels (b) and (c) show P′ = min(−log(p.t1d.meta)) for each densely typed region accessible on the ImmunoChip excluding the MHC and autosomal regions. Regions that overlap known T1D susceptibility regions are identified by blue bars, whereas yellow and pink show JIA and UC overlap respectively (
http://www.ImmunoBase.org– accessed February 13, 2014). Red bars denote shared overlap between T1D and focal disease. The y-axis is truncated for clarity. A fully interactive version of panels (b) and (c), along with further supporting resources are available at
http://www.immunobase.org/poster/type-1-diabetes-immunochip-study-onengut-gumuscu/.

Heat map showing chromatin state enrichment analysis of T1D 99% credible SNP set in ImmunoChip densely mapped regions versus the complement set, within Epigenomic Roadmap and ENCODE tissues. The top coloured row groups cell-types into 4 anatomical categories with relevance to type 1 diabetes, subsequent rows use a red (enrichment) to blue (depletion) scale to illustrate enrichment in a particular chromatin state (1_TssA – Active Tss, 2_TssAFlnk – Flanking Active TSS, 3_TxFlnk – Transcribed at gene 5′ and 3′, 4_Tx – Strong transcription, 5_TxWk – Weak transcription, 6_EnhG – Genic Enhancer, 7_Enh - Enhancer, 8_ZNF/Rpts – ZNF genes & repeats, 9_Het - Heterochromatin, 10_TssBiv- Bivalent/Poised TSS, 11_BivFlnk – Flanking Bivalent TSS/Enhancer, 12_EnhBiv – Bivalent enhancer, 13_RepPC – Repressed PolyComb, 14_RepPCWk – Weak repressed polycomb, 15_Quies – Quiescent/Low).
Similar articles
-
Kim SS, Hudgins AD, Yang J, Zhu Y, Tu Z, Rosenfeld MG, DiLorenzo TP, Suh Y. Kim SS, et al. PLoS One. 2021 Sep 16;16(9):e0257265. doi: 10.1371/journal.pone.0257265. eCollection 2021. PLoS One. 2021. PMID: 34529725 Free PMC article.
-
Contrasting the Genetic Background of Type 1 Diabetes and Celiac Disease Autoimmunity.
Gutierrez-Achury J, Romanos J, Bakker SF, Kumar V, de Haas EC, Trynka G, Ricaño-Ponce I, Steck A; Type 1 Diabetes Genetics Consortium; Chen WM, Onengut-Gumuscu S, Simsek S; Diabeter; Rewers M, Mulder CJ, Liu E, Rich SS, Wijmenga C. Gutierrez-Achury J, et al. Diabetes Care. 2015 Oct;38 Suppl 2(Suppl 2):S37-44. doi: 10.2337/dcs15-2007. Diabetes Care. 2015. PMID: 26405070 Free PMC article.
-
Robertson CC, Inshaw JRJ, Onengut-Gumuscu S, Chen WM, Santa Cruz DF, Yang H, Cutler AJ, Crouch DJM, Farber E, Bridges SL Jr, Edberg JC, Kimberly RP, Buckner JH, Deloukas P, Divers J, Dabelea D, Lawrence JM, Marcovina S, Shah AS, Greenbaum CJ, Atkinson MA, Gregersen PK, Oksenberg JR, Pociot F, Rewers MJ, Steck AK, Dunger DB; Type 1 Diabetes Genetics Consortium; Wicker LS, Concannon P, Todd JA, Rich SS. Robertson CC, et al. Nat Genet. 2021 Jul;53(7):962-971. doi: 10.1038/s41588-021-00880-5. Epub 2021 Jun 14. Nat Genet. 2021. PMID: 34127860 Free PMC article.
-
Mapping genes for autoimmunity in humans: type 1 diabetes as a model.
Onengut-Gumuscu S, Concannon P. Onengut-Gumuscu S, et al. Immunol Rev. 2002 Dec;190:182-94. doi: 10.1034/j.1600-065x.2002.19014.x. Immunol Rev. 2002. PMID: 12493015 Review.
-
Genetics and its potential to improve type 1 diabetes care.
Rich SS. Rich SS. Curr Opin Endocrinol Diabetes Obes. 2017 Aug;24(4):279-284. doi: 10.1097/MED.0000000000000347. Curr Opin Endocrinol Diabetes Obes. 2017. PMID: 28509690 Free PMC article. Review.
Cited by
-
[No authors listed] [No authors listed] Diabetes Care. 2015 Jan;38 Suppl:S1-2. doi: 10.2337/dc15-S001. Diabetes Care. 2015. PMID: 25537700 No abstract available.
-
Type 1 diabetes: genes associated with disease development.
Klak M, Gomółka M, Kowalska P, Cichoń J, Ambrożkiewicz F, Serwańska-Świętek M, Berman A, Wszoła M. Klak M, et al. Cent Eur J Immunol. 2020;45(4):439-453. doi: 10.5114/ceji.2020.103386. Epub 2021 Feb 7. Cent Eur J Immunol. 2020. PMID: 33658892 Free PMC article. Review.
-
Guo H, Fortune MD, Burren OS, Schofield E, Todd JA, Wallace C. Guo H, et al. Hum Mol Genet. 2015 Jun 15;24(12):3305-13. doi: 10.1093/hmg/ddv077. Epub 2015 Mar 5. Hum Mol Genet. 2015. PMID: 25743184 Free PMC article.
-
Genetic correlation between chronic sinusitis and autoimmune diseases.
Wang E, Sun Y, Zhao H, Wang M, Cao Z. Wang E, et al. Front Allergy. 2024 Sep 24;5:1387774. doi: 10.3389/falgy.2024.1387774. eCollection 2024. Front Allergy. 2024. PMID: 39381510 Free PMC article.
-
Abidha CA, Meeks KAC, Chilunga FP, Venema A, Schindlmayr R, Hayfron-Benjamin C, Klipstein-Grobusch K, Mockenhaupt FP, Agyemang C, Henneman P, Danquah I. Abidha CA, et al. Clin Epigenetics. 2024 Oct 16;16(1):143. doi: 10.1186/s13148-024-01758-z. Clin Epigenetics. 2024. PMID: 39415250 Free PMC article.
References
Publication types
MeSH terms
Substances
Grants and funding
- 100140/WT_/Wellcome Trust/United Kingdom
- R01 DK046635/DK/NIDDK NIH HHS/United States
- DP3 DK085678/DK/NIDDK NIH HHS/United States
- R01 DK096926/DK/NIDDK NIH HHS/United States
- DK046635/DK/NIDDK NIH HHS/United States
- 076113/WT_/Wellcome Trust/United Kingdom
- U01 DK062418/DK/NIDDK NIH HHS/United States
- MR/N01104X/1/MRC_/Medical Research Council/United Kingdom
- DK085678/DK/NIDDK NIH HHS/United States
- R01 HG004037/HG/NHGRI NIH HHS/United States
- WT061858/09115/WT_/Wellcome Trust/United Kingdom
- G1001799/MRC_/Medical Research Council/United Kingdom
- MC_U105261167/MRC_/Medical Research Council/United Kingdom
- 089989/WT_/Wellcome Trust/United Kingdom
- 091157/WT_/Wellcome Trust/United Kingdom
- WT_/Wellcome Trust/United Kingdom
LinkOut - more resources
Full Text Sources
Other Literature Sources
Medical